Two Cases of Tumor-induced Osteomalacia Resulting in Surgical Resection during Burosumab Therapy Article Swipe
Dai Nagata
,
Yuichi Takashi
,
Mayuko Yamamoto
,
Kyoko Toyokawa
,
Kiyoshi Makihata
,
Haruki Koganemaru
,
Saki Hideshima
,
Yoshimi Muta
,
Hisashi Yokomizo
,
Hironori Fukumoto
,
Shizuhide Nakayama
,
Hiroko Muta
,
Mikiko Aoki
,
Hiroshi Abe
,
Takuaki Yamamoto
,
Makoto Hamasaki
,
Daiji Kawanami
·
YOU?
·
· 2025
· Open Access
·
· DOI: https://doi.org/10.2169/internalmedicine.4958-24
YOU?
·
· 2025
· Open Access
·
· DOI: https://doi.org/10.2169/internalmedicine.4958-24
Tumor-induced osteomalacia (TIO) is a rare paraneoplastic syndrome that results from tumors that secrete fibroblast growth factor 23 (FGF23). This leads to chronic hypophosphatemia. Burosumab, an anti-FGF23 antibody, is an effective treatment when surgery is not possible; however, it complicates FGF23 measurements and postoperative monitoring. We describe the first case report of TIO in which the responsible tumors were discovered during burosumab therapy and successfully resected. Despite tumor removal, the serum FGF23 levels remained elevated. In the postoperative monitoring of patients treated with burosumab, physicians should focus on the serum and urine levels of phosphate rather than FGF23.
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Metadata
- Type
- article
- Language
- en
- Landing Page
- https://doi.org/10.2169/internalmedicine.4958-24
- OA Status
- diamond
- References
- 21
- Related Works
- 10
- OpenAlex ID
- https://openalex.org/W4408215287
All OpenAlex metadata
Raw OpenAlex JSON
- OpenAlex ID
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https://openalex.org/W4408215287Canonical identifier for this work in OpenAlex
- DOI
-
https://doi.org/10.2169/internalmedicine.4958-24Digital Object Identifier
- Title
-
Two Cases of Tumor-induced Osteomalacia Resulting in Surgical Resection during Burosumab TherapyWork title
- Type
-
articleOpenAlex work type
- Language
-
enPrimary language
- Publication year
-
2025Year of publication
- Publication date
-
2025-03-07Full publication date if available
- Authors
-
Dai Nagata, Yuichi Takashi, Mayuko Yamamoto, Kyoko Toyokawa, Kiyoshi Makihata, Haruki Koganemaru, Saki Hideshima, Yoshimi Muta, Hisashi Yokomizo, Hironori Fukumoto, Shizuhide Nakayama, Hiroko Muta, Mikiko Aoki, Hiroshi Abe, Takuaki Yamamoto, Makoto Hamasaki, Daiji KawanamiList of authors in order
- Landing page
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https://doi.org/10.2169/internalmedicine.4958-24Publisher landing page
- Open access
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YesWhether a free full text is available
- OA status
-
diamondOpen access status per OpenAlex
- OA URL
-
https://doi.org/10.2169/internalmedicine.4958-24Direct OA link when available
- Concepts
-
Medicine, Osteomalacia, Resection, Surgical resection, Surgery, General surgery, Radiology, Internal medicine, Vitamin D and neurologyTop concepts (fields/topics) attached by OpenAlex
- Cited by
-
0Total citation count in OpenAlex
- References (count)
-
21Number of works referenced by this work
- Related works (count)
-
10Other works algorithmically related by OpenAlex
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| abstract_inverted_index.which | 54 |
| abstract_inverted_index.FGF23. | 97 |
| abstract_inverted_index.during | 60 |
| abstract_inverted_index.factor | 16 |
| abstract_inverted_index.growth | 15 |
| abstract_inverted_index.levels | 72, 92 |
| abstract_inverted_index.rather | 95 |
| abstract_inverted_index.report | 50 |
| abstract_inverted_index.should | 85 |
| abstract_inverted_index.tumors | 11, 57 |
| abstract_inverted_index.Despite | 66 |
| abstract_inverted_index.chronic | 22 |
| abstract_inverted_index.results | 9 |
| abstract_inverted_index.secrete | 13 |
| abstract_inverted_index.surgery | 33 |
| abstract_inverted_index.therapy | 62 |
| abstract_inverted_index.treated | 81 |
| abstract_inverted_index.(FGF23). | 18 |
| abstract_inverted_index.describe | 46 |
| abstract_inverted_index.however, | 37 |
| abstract_inverted_index.patients | 80 |
| abstract_inverted_index.remained | 73 |
| abstract_inverted_index.removal, | 68 |
| abstract_inverted_index.syndrome | 7 |
| abstract_inverted_index.antibody, | 27 |
| abstract_inverted_index.burosumab | 61 |
| abstract_inverted_index.effective | 30 |
| abstract_inverted_index.elevated. | 74 |
| abstract_inverted_index.phosphate | 94 |
| abstract_inverted_index.possible; | 36 |
| abstract_inverted_index.resected. | 65 |
| abstract_inverted_index.treatment | 31 |
| abstract_inverted_index.Burosumab, | 24 |
| abstract_inverted_index.anti-FGF23 | 26 |
| abstract_inverted_index.burosumab, | 83 |
| abstract_inverted_index.discovered | 59 |
| abstract_inverted_index.fibroblast | 14 |
| abstract_inverted_index.monitoring | 78 |
| abstract_inverted_index.physicians | 84 |
| abstract_inverted_index.complicates | 39 |
| abstract_inverted_index.monitoring. | 44 |
| abstract_inverted_index.responsible | 56 |
| abstract_inverted_index.measurements | 41 |
| abstract_inverted_index.osteomalacia | 1 |
| abstract_inverted_index.successfully | 64 |
| abstract_inverted_index.Tumor-induced | 0 |
| abstract_inverted_index.postoperative | 43, 77 |
| abstract_inverted_index.paraneoplastic | 6 |
| abstract_inverted_index.hypophosphatemia. | 23 |
| cited_by_percentile_year | |
| countries_distinct_count | 1 |
| institutions_distinct_count | 17 |
| sustainable_development_goals[0].id | https://metadata.un.org/sdg/3 |
| sustainable_development_goals[0].score | 0.41999998688697815 |
| sustainable_development_goals[0].display_name | Good health and well-being |
| citation_normalized_percentile.value | 0.0957208 |
| citation_normalized_percentile.is_in_top_1_percent | False |
| citation_normalized_percentile.is_in_top_10_percent | False |